circRNA basic information
circBase ID: -
Name: hsa_circ_LINC00632
Synonym: CDR1as / ciRS-7
Host Gene: LINC00632
Genomic location(hg19): -
Genomic location(hg38): -
Subcellular localization: cytoplasm
 
 
 
 
 
 
 
Disease basic information
MONDO ID:
0019118
MONDO name: inherited retinal dystrophy
Disease details: retinal dystrophy
Disease DO ID:
8500, 8501
Disease MeSH ID:
D058499
Disease NCIt ID:
C35194; C35625
Disease ICD11 ID:
-
Disease OMIM ID:
-
Species: Human
Species details: Homo sapiens
Tissue specimen:

fibroblasts; retinal pigment epithelium; retinal organoids

Cell lines:

BJ (ATCC CRL-2522)

In vivo animal model:

-

circRNA-disease information
Expression pattern:
DN
Associated gene: Argonaute proteins, IGF2BP3
Associated microRNA: miR-7 / hsa-miR-7-5p
Biological function: Acts as a miR-7 sponge/reservoir; associated with dysregulation of miR-7 target genes in retinal organoids from retinal dystrophy families.
Molecular mechanism: Downregulation of CDR1as/ciRS-7 reduces miR-7 sequestration, consistent with increased miR-7 activity and dysregulation (mostly downregulation) of validated miR-7 target transcripts in retinal organoids.
Biological pathway or process:

ceRNA regulation (other)

Detected method:
Q
S
Validation methods:

RNA-seq; Back-Splice Junction PCR / divergent primers PCR; RT-qPCR; Transfection; Clinical Sample Validation; Bioinformatics Analysis

Clinical significance:

-

Description:

In X-linked inherited retinal dystrophy families with Xq27.1 inter-chromosomal insertions, CDR1as/ciRS-7 shows tissue-specific dysregulation and is down-regulated in retinal organoids and RPE. As a miR-7 sponge, reduced CDR1as/ciRS-7 is associated with dysregulation of validated miR-7 target transcripts, supporting a circRNA/miRNA/mRNA mechanism contributing to disease.

Confidence score:

0.5922

Other information
Title:

Inter-chromosomal insertions at Xq27.1 associated with retinal dystrophy induce dysregulation of LINC00632 and CDR1as/ciRS-7.

Journal: American journal of human genetics
Published: 2025
PubMed ID: 39892393
Study type:

combined biological and clinical study

Data availability: NGS data supporting the current study have not been deposited in a public repository; Supplemental information can be found online at https://doi.org/10.1016/j.ajhg.2025.01.007.
Code availability: -